Tonsil tissue not located at known anatomical locations at the entry of aero-digestive system is called ectopic tonsil. This is rarely presented clinically and may lead to diagnostic confusion when encountered. The diagnosis of ectopic tonsil is challenging as it is usually asymptomatic and requires histopathological examination for definitive diagnosis. A case of patient with sublingual ectopic tonsillar tissue is described here. Otolaryngologists colleagues are encouraged to pay attention to this entity and consider it in the differential diagnosis of an unclear lump in the head and neck region especially, in the oral cavity.